FDA Accepts UniQure's AMT-130 Gene Therapy Application for Huntington's Disease, Decision Expected May 2027

November 2, 2026
FDA Accepts UniQure's AMT-130 Gene Therapy Application for Huntington's Disease, Decision Expected May 2027
  • UniQure announced that the FDA has accepted the marketing application for AMT-130 gene therapy to treat Huntington’s disease, with an expected decision date of May 1, 2027, and an advisory committee review is tentatively planned.

  • If approved, ifezuntirgene inilparvovec would be the first disease-modifying treatment for Huntington’s disease and has FDA Breakthrough Therapy and RMAT designations, as well as Fast Track designation.

  • The FDA accepted for review and granted Priority Review to the Biologics License Application for ifezuntirgene inilparvovec, with a PDUFA target action date of May 1, 2027.

  • In September 2026, four-year data were weaker than expected, contributing to stock declines, but the company emphasized the importance of the ongoing regulatory process.

  • Analysis of the mitochondrial replacement topic is behind a STAT+ paywall, limiting detailed public reporting and context.

  • The press release includes forward-looking statements and outlines regulatory, confirmatory data, and post-approval risks.

  • The Phase I/II program dosed 51 patients across multiple cohorts, including a U.S. randomized study and a European open-label study, with additional cohorts exploring dose combinations and immunosuppression.

  • UniQure provides investor and media contact details and references clinical trial identifiers NCT05243017 and NCT04120493.

  • Earlier in 2025, the FDA reversed a prior stance after three-year data, saying the data were not adequate primary evidence for a BLA submission, contributing to a volatile regulatory path.

  • The confirmatory trial remains a key priority, with screening expected to begin by year-end and about 200 patients to be enrolled, comparing AMT-130 to standard of care over 36 months to assess total functional capacity.

  • The BLA relies on 36-month Phase I/II data using a propensity score-matched external control, with a planned confirmatory trial of about 200 patients in a 2:1 randomization, primary endpoint Total Functional Capacity at 36 months.

  • Overall development has been rocky, but regulatory momentum centers on the May 1 decision date and potential advisory committee discussion.

Summary based on 3 sources


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